Characterization of the mitochondrial cell death pathways in C. elegans

 

The identification of CPS-6/EndoG, an apoptotic nuclease from mitochondria

 

Mitochondrial endonuclease G is important for apoptosis in C. elegans

 

JAY PARRISH*, LILY LI , KRISTINA KLOTZ*, DUNCAN LEDWICH*, XIAODONG WANG  & DING XUE*

 

* Department of Molecular, Cellular, and Developmental Biology, University of Colorado, Boulder, Colorado 80309, USA

  Howard Hughes Medical Institute and Department of Biochemistry, University of Texas Southwestern Medical Center, Dallas, Texas 75390, USA

 

Programmed cell death (apoptosis) is a tightly regulated process of cell disassembly in which dying cells and their nuclei shrink and fragment and the chromosomal DNA is degraded into internucleosomal repeats. Here we report the characterization of the cps-6 gene, which appears to function downstream of, or in parallel to, the cell-death protease CED-3 of Caenorhabditis elegans in the DNA degradation process during apoptosis. cps-6 encodes a homologue of human mitochondrial endonuclease G, and its protein product similarly localizes to mitochondria in C. elegans. Reduction of cps-6 activity caused by a genetic mutation or RNA-mediated interference (RNAi) affects normal DNA degradation, as revealed by increased staining in a TUNEL assay, and results in delayed appearance of cell corpses during development in C. elegans. This observation provides in vivo evidence that the DNA degradation process is important for proper progression of apoptosis. CPS-6 is the first mitochondrial protein identified to be involved in programmed cell death in C. elegans, underscoring the conserved and important role of mitochondria in the execution of apoptosis.

 

Parrish, J., Li, L., Klotz, K., Ledwich, D., Wang, X.D., and Xue, D. (2001).  C. elegans mitochondrial endonuclease G is important for apoptosis.  Nature 412, 90-94. (Abstract and PDF).

 

 

WAH-1, a C. elegans AIF homologue, cooperates with CPS-6/EndoG to regulates apoptotic DNA degradation.

 

Mechanisms of AIF-mediated apoptotic DNA degradation in Caenorhabditis elegans

 

Xiaochen Wang,1 Chonglin Yang,1 Jijie Chai,2 Yigong Shi,2 Ding Xue1

1 Department of Molecular, Cellular and Developmental Biology, University of

Colorado, Boulder, CO 80309, USA

2 Department of Molecular Biology, Princeton University, Princeton, NJ 08544, USA

 

Apoptosis-inducing factor (AIF), a mitochondrial oxidoreductase, is released into the cytoplasm to induce cell death in response to apoptotic signals. However, the mechanisms underlying this process have not been resolved. We report that inactivation of the Caenorhabditis elegans AIF homolog wah-1 by RNA interference delayed the normal progression of apoptosis and caused a defect in apoptotic DNA degradation. WAH-1 localized in C. elegans mitochondria and was released into the cytosol and nucleus by the BH3-domain protein EGL-1 in a caspase (CED-3)-dependent manner.  In addition, WAH-1 associated and cooperated with the mitochondrial endonuclease CPS-6/endonuclease G (EndoG) to promote DNA degradation and apoptosis. Thus, AIF and EndoG define a single, mitochondria-initiated apoptotic DNA degradation pathway that is conserved between C. elegans and mammals.

 

Wang, X.C., Yang, C.L., Cai, J.J., Shi, Y.G., and Xue, D. (2002).  Mechanisms of AIF-mediated apoptotic DNA degradation in Caenorhabditis elegans.  Science 298, 1587-1592.  (Abstract and PDF).

 

 

WAH-1 also promotes phosphatidylserine externalization in apoptotic cells through SCRM-1

C. elegans mitochondrial factor WAH-1 promotes phosphatidylserine externalization in apoptotic cells through phospholipid scramblase SCRM-1

Xiaochen Wang1, Jin Wang2, Keiko Gengyo-Ando3, Lichuan Gu4, Chun-Ling Sun1, Chonglin Yang1, Yong Shi1, Tetsuo Kobayashi3, Yigong Shi4, Shohei Mitani3, Xiao-Song Xie2 & Ding Xue1

1  Department of Molecular, Cellular, and Developmental Biology, University of Colorado, Boulder, CO 80309, USA.

2  McDermott Center for Human Growth and Development, University of Texas Southwestern Medical Center, Dallas, TX 75390, USA.

3  Department of Physiology, Tokyo Women's Medical University, School of Medicine, and CREST, JST, Tokyo, 162-8666, Japan.

4  Department of Molecular Biology, Princeton University, Princeton, NJ 08544, USA.

 

Externalization of phosphatidylserine, which is normally restricted to the inner leaflet of plasma membrane, is a hallmark of mammalian apoptosis. It is not known what activates and mediates the phosphatidylserine externalization process in apoptotic cells. Here, we report the development of an annexin V-based phosphatidylserine labelling method and show that a majority of apoptotic germ cells in Caenorhabditis elegans have surface-exposed phosphatidylserine, indicating that phosphatidylserine externalization is a conserved apoptotic event in worms. Importantly, inactivation of the gene encoding either the C. elegans apoptosis-inducing factor (AIF) homologue (WAH-1)5, a mitochondrial apoptogenic factor, or the C. elegans phospholipid scramblase 1 (SCRM-1), a plasma membrane protein, reduces phosphatidylserine exposure on the surface of apoptotic germ cells and compromises cell-corpse engulfment. WAH-1 associates with SCRM-1 and activates its phospholipid scrambling activity in vitro. Thus WAH-1, after its release from mitochondria during apoptosis, promotes plasma membrane phosphatidylserine externalization through its downstream effector, SCRM-1.

Wang, X.C., Wang, J., Gengyo-Ando, K., Gu, L.C., Sun, C.L., Yang, C.L., Shi, Y., Kobayashi, T., Shi, Y.G., Mitani, S., Xie, X.S., and Xue, D. (2007). "C. elegans mitochondrial factor WAH-1 promotes phosphatidylserine externalization in apoptotic cells through phospholipid scramblase SCRM-1". Nature Cell Biology 9, 541-549. (Abstract and PDF).

 

For detailed review on mitochondrial cell death pathways and studies

 

Breckenridge, D. and Xue, D. (2004). Regulation of mitochondrial membrane permeabilization by BCL-2 family proteins and caspases. Curr.  Opin. Cell Biol. 16, 647-652. (Abstract and PDF)